Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations

<h3>Background</h3><p dir="ltr">Neuromyelitis Optica Spectrum Disorder is a span of neuro-inflammatory diseases with observed predilection towards causing optic neuritis, longitudinally extensive transverse myelitis, area postrema syndrome, and diencephalon syndrome. Desp...

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Main Author: Abeer Sabry Safan (14778022) (author)
Other Authors: Wanis H Ibrahim (14631239) (author), Mahfoud Elbashari (17870498) (author), Gholam Adeli (14777560) (author)
Published: 2023
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author Abeer Sabry Safan (14778022)
author2 Wanis H Ibrahim (14631239)
Mahfoud Elbashari (17870498)
Gholam Adeli (14777560)
author2_role author
author
author
author_facet Abeer Sabry Safan (14778022)
Wanis H Ibrahim (14631239)
Mahfoud Elbashari (17870498)
Gholam Adeli (14777560)
author_role author
dc.creator.none.fl_str_mv Abeer Sabry Safan (14778022)
Wanis H Ibrahim (14631239)
Mahfoud Elbashari (17870498)
Gholam Adeli (14777560)
dc.date.none.fl_str_mv 2023-01-01T00:00:00Z
dc.identifier.none.fl_str_mv 10.1016/j.nerep.2023.100168
dc.relation.none.fl_str_mv https://figshare.com/articles/journal_contribution/Neuromyelitis_optica_spectrum_disorder_and_enterovirus-71_infection_A_perplexing_neurological_constellations/25108037
dc.rights.none.fl_str_mv CC BY 4.0
info:eu-repo/semantics/openAccess
dc.subject.none.fl_str_mv Biomedical and clinical sciences
Clinical sciences
Brainstem syndrome
area of postrema
NMOSD
Optic neuritis
Myelitis
Enterovirus-71
dc.title.none.fl_str_mv Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
dc.type.none.fl_str_mv Text
Journal contribution
info:eu-repo/semantics/publishedVersion
text
contribution to journal
description <h3>Background</h3><p dir="ltr">Neuromyelitis Optica Spectrum Disorder is a span of neuro-inflammatory diseases with observed predilection towards causing optic neuritis, longitudinally extensive transverse myelitis, area postrema syndrome, and diencephalon syndrome. Despite the revolutionizing discovery of its biomarker (Aquaporin-4-IgG-antibodies), its pathogenesis and possible para-infectious immunogenic triggers are rarely reported and not fully understood.</p><p><br></p><h3>Clinical presentation</h3><p dir="ltr">We report a case of Neuromyelitis Optica Spectrum Disorder with positive serum aquaporin-4-IgG-antibodies presenting with severe area postrema syndrome for a month followed by one-week of rapid constellations of extensive brainstem syndrome, transverse myelitis, and left optic neuritis. Magnetic Resonance Imaging of the brain and spine revealed left optic neuritis with multilevel patchy areas of intra-axial high T2- signal of the central and dorsal aspect of the medulla oblongata and cervical-thoracic spinal cord with mild patchy postcontrast enhancement in the lower medulla Interestingly, his illness was preceded by fever and flu-like symptoms and a nasopharyngeal swab polymerase chain reaction was positive for Enterovirus-71. The patient's condition gradually improved with remarkable recovery at nine-week mark. He was treated with plasmapheresis, intravenous pulsed methylprednisolone, an intensive six-week rehabilitation program followed by rituximab.</p><p><br></p><h3>Conclusions</h3><p dir="ltr">Multiple viral infections have been reported to induce Neuromyelitis Optica Spectrum Disorder. To the best of our knowledge, Enterovirus-71 has never been reported to induce this disorder despite its well-reported association with brainstem syndromes and rhombencephalitis. We postulate that this virus has induced immune-cross reactivity that triggered aquaporin-4-IgG-antibodies in our patient which warrants further research.</p><h2>Other Information</h2><p dir="ltr">Published in: Neuroimmunology Reports<br>License: <a href="http://creativecommons.org/licenses/by/4.0/" target="_blank">http://creativecommons.org/licenses/by/4.0/</a><br>See article on publisher's website: <a href="https://dx.doi.org/10.1016/j.nerep.2023.100168" target="_blank">https://dx.doi.org/10.1016/j.nerep.2023.100168</a></p>
eu_rights_str_mv openAccess
id Manara2_88d4b8c85dd053d2be2c66bde8c134e2
identifier_str_mv 10.1016/j.nerep.2023.100168
network_acronym_str Manara2
network_name_str Manara2
oai_identifier_str oai:figshare.com:article/25108037
publishDate 2023
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rights_invalid_str_mv CC BY 4.0
spelling Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellationsAbeer Sabry Safan (14778022)Wanis H Ibrahim (14631239)Mahfoud Elbashari (17870498)Gholam Adeli (14777560)Biomedical and clinical sciencesClinical sciencesBrainstem syndromearea of postremaNMOSDOptic neuritisMyelitisEnterovirus-71<h3>Background</h3><p dir="ltr">Neuromyelitis Optica Spectrum Disorder is a span of neuro-inflammatory diseases with observed predilection towards causing optic neuritis, longitudinally extensive transverse myelitis, area postrema syndrome, and diencephalon syndrome. Despite the revolutionizing discovery of its biomarker (Aquaporin-4-IgG-antibodies), its pathogenesis and possible para-infectious immunogenic triggers are rarely reported and not fully understood.</p><p><br></p><h3>Clinical presentation</h3><p dir="ltr">We report a case of Neuromyelitis Optica Spectrum Disorder with positive serum aquaporin-4-IgG-antibodies presenting with severe area postrema syndrome for a month followed by one-week of rapid constellations of extensive brainstem syndrome, transverse myelitis, and left optic neuritis. Magnetic Resonance Imaging of the brain and spine revealed left optic neuritis with multilevel patchy areas of intra-axial high T2- signal of the central and dorsal aspect of the medulla oblongata and cervical-thoracic spinal cord with mild patchy postcontrast enhancement in the lower medulla Interestingly, his illness was preceded by fever and flu-like symptoms and a nasopharyngeal swab polymerase chain reaction was positive for Enterovirus-71. The patient's condition gradually improved with remarkable recovery at nine-week mark. He was treated with plasmapheresis, intravenous pulsed methylprednisolone, an intensive six-week rehabilitation program followed by rituximab.</p><p><br></p><h3>Conclusions</h3><p dir="ltr">Multiple viral infections have been reported to induce Neuromyelitis Optica Spectrum Disorder. To the best of our knowledge, Enterovirus-71 has never been reported to induce this disorder despite its well-reported association with brainstem syndromes and rhombencephalitis. We postulate that this virus has induced immune-cross reactivity that triggered aquaporin-4-IgG-antibodies in our patient which warrants further research.</p><h2>Other Information</h2><p dir="ltr">Published in: Neuroimmunology Reports<br>License: <a href="http://creativecommons.org/licenses/by/4.0/" target="_blank">http://creativecommons.org/licenses/by/4.0/</a><br>See article on publisher's website: <a href="https://dx.doi.org/10.1016/j.nerep.2023.100168" target="_blank">https://dx.doi.org/10.1016/j.nerep.2023.100168</a></p>2023-01-01T00:00:00ZTextJournal contributioninfo:eu-repo/semantics/publishedVersiontextcontribution to journal10.1016/j.nerep.2023.100168https://figshare.com/articles/journal_contribution/Neuromyelitis_optica_spectrum_disorder_and_enterovirus-71_infection_A_perplexing_neurological_constellations/25108037CC BY 4.0info:eu-repo/semantics/openAccessoai:figshare.com:article/251080372023-01-01T00:00:00Z
spellingShingle Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
Abeer Sabry Safan (14778022)
Biomedical and clinical sciences
Clinical sciences
Brainstem syndrome
area of postrema
NMOSD
Optic neuritis
Myelitis
Enterovirus-71
status_str publishedVersion
title Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
title_full Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
title_fullStr Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
title_full_unstemmed Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
title_short Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
title_sort Neuromyelitis optica spectrum disorder and enterovirus-71 infection: A perplexing neurological constellations
topic Biomedical and clinical sciences
Clinical sciences
Brainstem syndrome
area of postrema
NMOSD
Optic neuritis
Myelitis
Enterovirus-71