Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods

<p></p><div> <p>In evidence synthesis, dealing with zero-events studies is an important and complicated task that has generated broad discussion. Numerous methods provide valid solutions to synthesizing data from studies with zero-events, either based on a frequentist or a Ba...

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Main Author: Chang Xu (102022) (author)
Other Authors: Luis Furuya‐Kanamori (14778820) (author), Lifeng Lin (2034385) (author)
Published: 2023
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author Chang Xu (102022)
author2 Luis Furuya‐Kanamori (14778820)
Lifeng Lin (2034385)
author2_role author
author
author_facet Chang Xu (102022)
Luis Furuya‐Kanamori (14778820)
Lifeng Lin (2034385)
author_role author
dc.creator.none.fl_str_mv Chang Xu (102022)
Luis Furuya‐Kanamori (14778820)
Lifeng Lin (2034385)
dc.date.none.fl_str_mv 2023-03-16T06:23:50Z
dc.identifier.none.fl_str_mv 10.1002/jrsm.1521
dc.relation.none.fl_str_mv https://figshare.com/articles/journal_contribution/Synthesis_of_evidence_from_zero_events_studies_A_comparison_of_one_stage_framework_methods/22258243
dc.rights.none.fl_str_mv CC BY 4.0
info:eu-repo/semantics/openAccess
dc.subject.none.fl_str_mv Mathematical sciences
Statistics
Education
dc.title.none.fl_str_mv Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
dc.type.none.fl_str_mv Text
Journal contribution
info:eu-repo/semantics/publishedVersion
text
contribution to journal
description <p></p><div> <p>In evidence synthesis, dealing with zero-events studies is an important and complicated task that has generated broad discussion. Numerous methods provide valid solutions to synthesizing data from studies with zero-events, either based on a frequentist or a Bayesian framework. Among frequentist frameworks, the one-stage methods have their unique advantages to deal with zero-events studies, especially for double-arm-zero-events. In this article, we give a concise overview of the one-stage frequentist methods. We conducted simulation studies to compare the statistical properties of these methods to the two-stage frequentist method (continuity correction) for meta-analysis with zero-events studies when double-zero-events studies were included. Our simulation studies demonstrated that the generalized estimating equation with unstructured correlation and beta-binomial method had the best performance among the one-stage methods. The random intercepts generalized linear mixed model showed good performance in the absence of obvious between-study variance. Our results also showed that the continuity correction with inverse-variance heterogeneous (IVhet) analytic model based on the two-stage framework had good performance when the between-study variance was obvious and the group size was balanced for included studies. In summary, the one-stage framework has unique advantages to deal with studies with zero events and is not susceptive to group size ratio. It should be considered in future meta-analyses whenever possible.</p> </div><p></p><h2>Other Information</h2> <p> Published in: Research Synthesis Methods<br> License: <a href="http://creativecommons.org/licenses/by/4.0/" target="_blank">http://creativecommons.org/licenses/by/4.0/</a><br>See article on publisher's website: <a href="http://dx.doi.org/10.1002/jrsm.1521" target="_blank">http://dx.doi.org/10.1002/jrsm.1521</a></p>
eu_rights_str_mv openAccess
id Manara2_b43148d99d668cfc0588dbc51c08c5cd
identifier_str_mv 10.1002/jrsm.1521
network_acronym_str Manara2
network_name_str Manara2
oai_identifier_str oai:figshare.com:article/22258243
publishDate 2023
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repository.name.fl_str_mv
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rights_invalid_str_mv CC BY 4.0
spelling Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methodsChang Xu (102022)Luis Furuya‐Kanamori (14778820)Lifeng Lin (2034385)Mathematical sciencesStatisticsEducation<p></p><div> <p>In evidence synthesis, dealing with zero-events studies is an important and complicated task that has generated broad discussion. Numerous methods provide valid solutions to synthesizing data from studies with zero-events, either based on a frequentist or a Bayesian framework. Among frequentist frameworks, the one-stage methods have their unique advantages to deal with zero-events studies, especially for double-arm-zero-events. In this article, we give a concise overview of the one-stage frequentist methods. We conducted simulation studies to compare the statistical properties of these methods to the two-stage frequentist method (continuity correction) for meta-analysis with zero-events studies when double-zero-events studies were included. Our simulation studies demonstrated that the generalized estimating equation with unstructured correlation and beta-binomial method had the best performance among the one-stage methods. The random intercepts generalized linear mixed model showed good performance in the absence of obvious between-study variance. Our results also showed that the continuity correction with inverse-variance heterogeneous (IVhet) analytic model based on the two-stage framework had good performance when the between-study variance was obvious and the group size was balanced for included studies. In summary, the one-stage framework has unique advantages to deal with studies with zero events and is not susceptive to group size ratio. It should be considered in future meta-analyses whenever possible.</p> </div><p></p><h2>Other Information</h2> <p> Published in: Research Synthesis Methods<br> License: <a href="http://creativecommons.org/licenses/by/4.0/" target="_blank">http://creativecommons.org/licenses/by/4.0/</a><br>See article on publisher's website: <a href="http://dx.doi.org/10.1002/jrsm.1521" target="_blank">http://dx.doi.org/10.1002/jrsm.1521</a></p>2023-03-16T06:23:50ZTextJournal contributioninfo:eu-repo/semantics/publishedVersiontextcontribution to journal10.1002/jrsm.1521https://figshare.com/articles/journal_contribution/Synthesis_of_evidence_from_zero_events_studies_A_comparison_of_one_stage_framework_methods/22258243CC BY 4.0info:eu-repo/semantics/openAccessoai:figshare.com:article/222582432023-03-16T06:23:50Z
spellingShingle Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
Chang Xu (102022)
Mathematical sciences
Statistics
Education
status_str publishedVersion
title Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
title_full Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
title_fullStr Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
title_full_unstemmed Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
title_short Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
title_sort Synthesis of evidence from zero‐events studies: A comparison of one‐stage framework methods
topic Mathematical sciences
Statistics
Education